A novel CLTC-FOSB gene fusion in pseudomyogenic hemangioendothelioma of bone

Genes Chromosomes Cancer. 2021 Jan;60(1):38-42. doi: 10.1002/gcc.22891. Epub 2020 Aug 22.

Abstract

Pseudomyogenic hemangioendothelioma, an uncommon mesenchymal neoplasm composed of plump spindled and/or epithelioid endothelial cells, may present multicentrically and tends to locally recur but rarely metastasizes. Morphologic resemblance to epithelioid sarcoma and other spindle cell neoplasms may result in diagnostic confusion. Molecular characterization of pseudomyogenic hemangioendothelioma has revealed these neoplasms often harbor a rearrangement of the FOSB gene with SERPINE1 or ACTB as recurrent fusion gene partners. Herein, a case of a fibular pseudomyogenic hemangioendothelioma with minimal extension into the adjacent soft tissue arising in a 17 year-old male is presented. The neoplasm exhibited sheets of epithelioid cells with abundant eosinophilic cytoplasm and variably eccentric nuclei. RNA sequencing revealed a novel CLTC-FOSB fusion transcript that was subsequently confirmed by direct sequencing of reverse transcription-polymerase chain reaction products demonstrating an in-frame fusion between exon 17 of the clathrin heavy chain (CLTC) gene and exon 2 of the FOSB (FosB proto-oncogene, AP-1 transcription factor subunit) gene. CLTC-FOSB fusion has not been described in a neoplasm before.

Keywords: CLTC; FOSB; pseudomyogenic hemangioendothelioma.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Bone Neoplasms / genetics*
  • Bone Neoplasms / pathology
  • Clathrin Heavy Chains / genetics*
  • Clathrin Heavy Chains / metabolism
  • Hemangioendothelioma / genetics*
  • Hemangioendothelioma / pathology
  • Humans
  • Male
  • Oncogene Proteins, Fusion / genetics*
  • Oncogene Proteins, Fusion / metabolism
  • Proto-Oncogene Mas
  • Proto-Oncogene Proteins c-fos / genetics*
  • Proto-Oncogene Proteins c-fos / metabolism
  • RNA, Messenger / genetics
  • RNA, Messenger / metabolism

Substances

  • CLTC protein, human
  • FOSB protein, human
  • MAS1 protein, human
  • Oncogene Proteins, Fusion
  • Proto-Oncogene Mas
  • Proto-Oncogene Proteins c-fos
  • RNA, Messenger
  • Clathrin Heavy Chains