Sudden infant death from neonate carnitine palmitoyl transferase II deficiency

Forensic Sci Int. 2017 Sep:278:e41-e44. doi: 10.1016/j.forsciint.2017.06.020. Epub 2017 Jun 27.

Abstract

A full-term female baby born to parents who gave birth three years prior to a girl who survived only 31h postpartum died 36h after birth. An autopsy showed that the heart was markedly hypertrophic (32g). Microscopically, the myocardium, liver and kidney cells exhibited extensive vacuolar degeneration. Sudan III staining was positive in cardiac muscle, liver and kidney tissue. Tandem mass spectrometry analysis revealed that the deceased patient had a carnitine palmitoyl transferase II (CPT2) deficiency or a carnitine-acylcarnitine translocase deficiency. Genetic testing of the parents revealed heterozygous CPT2 mutations, indicating that their offspring would have a 25% chance of having a CPT2 deficiency. Therefore, we speculated that CPT2 deficiency might be the cause of death based on the results of staining, tandem mass spectrometry analysis and parental genetic testing.

Keywords: Carnitine palmitoyl transferase II deficiency; Cell steatosis; Genetic test; Sudden death in infancy.

Publication types

  • Case Reports

MeSH terms

  • Carnitine O-Palmitoyltransferase / deficiency*
  • Carnitine O-Palmitoyltransferase / genetics
  • Female
  • Genetic Testing
  • Heterozygote
  • Humans
  • Infant, Newborn
  • Kidney / pathology
  • Liver / pathology
  • Metabolism, Inborn Errors / diagnosis*
  • Metabolism, Inborn Errors / genetics
  • Mutation
  • Myocardium / pathology
  • Sudden Infant Death / etiology*
  • Vacuoles / pathology

Substances

  • Carnitine O-Palmitoyltransferase

Supplementary concepts

  • Carnitine palmitoyl transferase 2 deficiency