Differentiation-dependent requirement of Tsix long non-coding RNA in imprinted X-chromosome inactivation

Nat Commun. 2014 Jun 30:5:4209. doi: 10.1038/ncomms5209.

Abstract

Imprinted X-inactivation is a paradigm of mammalian transgenerational epigenetic regulation resulting in silencing of genes on the paternally inherited X-chromosome. The preprogrammed fate of the X-chromosomes is thought to be controlled in cis by the parent-of-origin-specific expression of two opposing long non-coding RNAs, Tsix and Xist, in mice. Exclusive expression of Tsix from the maternal-X has implicated it as the instrument through which the maternal germline prevents inactivation of the maternal-X in the offspring. Here, we show that Tsix is dispensable for inhibiting Xist and X-inactivation in the early embryo and in cultured stem cells of extra-embryonic lineages. Tsix is instead required to prevent Xist expression as trophectodermal progenitor cells differentiate. Despite induction of wild-type Xist RNA and accumulation of histone H3-K27me3, many Tsix-mutant X-chromosomes fail to undergo ectopic X-inactivation. We propose a novel model of lncRNA function in imprinted X-inactivation that may also apply to other genomically imprinted loci.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Cell Differentiation*
  • Female
  • Genomic Imprinting*
  • Male
  • Mice / embryology
  • Mice / genetics*
  • Mice / metabolism
  • RNA, Long Noncoding / genetics
  • RNA, Long Noncoding / metabolism*
  • Stem Cells / cytology
  • Stem Cells / metabolism
  • Trophoblasts / cytology
  • Trophoblasts / metabolism
  • X Chromosome / genetics*
  • X Chromosome Inactivation*

Substances

  • RNA, Long Noncoding
  • Tsix transcript, mouse
  • XIST non-coding RNA