Dyskinesias as the neurologic complications of hematologic disorders were described in detail on abetalipoproteinemia and ataxia telangiectasia as well as in summary on other hematologic diseases. Dyskinesias as the iatrogenic neurologic manifestations in hematologic disorders were also briefly described. Although the pathogenetic mechanisms of dyskinesias observed in hematologic disorders were quite heterogeneous, they could provide us with good suggestions and clues to clarify the true mechanisms of their own as well as other dyskinesias.