CCDC88B is a novel regulator of maturation and effector functions of T cells during pathological inflammation

J Exp Med. 2014 Dec 15;211(13):2519-35. doi: 10.1084/jem.20140455. Epub 2014 Nov 17.

Abstract

We used a genome-wide screen in mutagenized mice to identify genes which inactivation protects against lethal neuroinflammation during experimental cerebral malaria (ECM). We identified an ECM-protective mutation in coiled-coil domain containing protein 88b (Ccdc88b), a poorly annotated gene that is found expressed specifically in spleen, bone marrow, lymph nodes, and thymus. The CCDC88B protein is abundantly expressed in immune cells, including both CD4(+) and CD8(+) T lymphocytes, and in myeloid cells, and loss of CCDC88B protein expression has pleiotropic effects on T lymphocyte functions, including impaired maturation in vivo, significantly reduced activation, reduced cell division as well as impaired cytokine production (IFN-γ and TNF) in response to T cell receptor engagement, or to nonspecific stimuli in vitro, and during the course of P. berghei infection in vivo. This identifies CCDC88B as a novel and important regulator of T cell function. The human CCDC88B gene maps to the 11q13 locus that is associated with susceptibility to several inflammatory and auto-immune disorders. Our findings strongly suggest that CCDC88B is the morbid gene underlying the pleiotropic effect of the 11q13 locus on inflammation.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Base Sequence
  • Carrier Proteins / genetics*
  • Carrier Proteins / metabolism
  • Cell Differentiation*
  • Chromosomes, Human, Pair 11 / genetics
  • Disease Resistance / immunology
  • Ethylnitrosourea
  • Female
  • Gene Expression Regulation
  • Genetic Association Studies
  • Hematopoietic System / metabolism
  • Humans
  • Inflammation / immunology*
  • Inflammation / pathology*
  • Lymphocyte Activation / immunology
  • Malaria, Cerebral / genetics
  • Malaria, Cerebral / immunology
  • Malaria, Cerebral / parasitology
  • Malaria, Cerebral / prevention & control
  • Male
  • Mice, Inbred C57BL
  • Mice, Mutant Strains
  • Molecular Sequence Data
  • Mutation / genetics
  • Myeloid Cells / metabolism
  • Organ Specificity / genetics
  • Plasmodium berghei
  • RNA, Messenger / genetics
  • RNA, Messenger / metabolism
  • Receptors, Antigen, T-Cell / metabolism
  • T-Lymphocytes / cytology*
  • T-Lymphocytes / immunology*

Substances

  • Carrier Proteins
  • RNA, Messenger
  • Receptors, Antigen, T-Cell
  • coiled-coil domain containing 88B protein, mouse
  • Ethylnitrosourea