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Orbit. 2012 Oct;31(5):321-3. doi: 10.3109/01676830.2012.678547. Epub 2012 May 29.

Acute orbital inflammatory syndrome secondary to an ANCA-positive small-vessel vasculitis: a case report and review of the literature.

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1
Department of Ophthalmology, Dalhousie University , Halifax , Canada. babak.maleki@gmail.com

Abstract

A 61-year-old man presents with sequential painful bilateral proptosis within 36 h and orbital compartment syndrome resulting in complete loss of vision bilaterally. Sequential urgent lateral canthotomy and cantholysis were performed to reverse the compartment syndrome. Orbital imaging showed non-specific orbital inflammation. Biopsies showed necrotizing inflammation and bloodwork was positive for c-ANCA. The patient was therefore treated with prednisone and cyclophosphomide and showed good recovery of vision in one eye, and had no recurrence of orbital inflammation. ANCA-associated orbital vasculitides are rare, but must be kept in mind in the differential diagnosis of acute orbital inflammatory syndromes.

PMID:
22642696
DOI:
10.3109/01676830.2012.678547
[Indexed for MEDLINE]
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