Familial caudal dysgenesis: evidence for a major dominant gene

Clin Genet. 1990 Sep;38(3):170-5. doi: 10.1111/j.1399-0004.1990.tb03567.x.

Abstract

Four sibs with varying degrees of caudal dysgenesis are described. Case 1 showed aberrant umbilical cord vasculature with a single umbilical artery near the placental insertion. Cases 2 and 3 showed full sirenomelia, one with a complex congenital heart defect. Case 4 had an imperforate anus and an excessively long umbilical cord. The father's half-sib had an imperforate anus, rectovaginal fistula and genitourinary anomalies. A dominant gene with reduced penetrance is likely.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Abnormalities, Multiple / genetics
  • Anus, Imperforate / genetics*
  • Consanguinity
  • Ectromelia / genetics*
  • Female
  • Fetal Death / genetics
  • Genes, Dominant*
  • Humans
  • Infant, Newborn
  • Pedigree
  • Syndrome
  • Umbilical Arteries / abnormalities*