Primary pulmonary hyalinizing clear cell carcinoma of bronchial submucosal gland origin

Hum Pathol. 2015 Mar;46(3):471-5. doi: 10.1016/j.humpath.2014.11.010. Epub 2014 Nov 26.

Abstract

Hyalinizing clear cell carcinoma (HCCC) has only been described in salivary glands of the head and neck. We report a 38-year-old man with a 2.6-cm lung tumor that was growing in a peribronchial location and had morphologic features of HCCC. The tumor cells expressed cytokeratin 7 and keratin AE1/AE3, and the vast majority of tumor cells marked also with p63 and p40. They were negative for cytokeratin 20, S-100, smooth muscle actin, napsin A, and thyroid transcription factor-1. Fluorescence in situ hybridization revealed Ewing Sarcoma Breakpoint Region 1 (EWSR1) rearrangement, and reverse-transcription polymerase chain reaction confirmed the presence of the EWSR1-Activating Transcription Factor 1 (ATF1) fusion transcript, which was subsequently sequenced. The morphologic, immunophenotypic, cytogenetic, and molecular findings together with the patient's history and location of the tumor support a diagnosis of primary pulmonary HCCC of bronchial submucosal gland origin. It is our understanding that this is the first report of HCCC arising as a primary tumor outside the head and neck region.

Keywords: EWSR1 rearrangement; EWSR1-ATF1 fusion; FISH; RT-PCR; Salivary gland neoplasm.

Publication types

  • Case Reports

MeSH terms

  • Adenocarcinoma, Clear Cell / chemistry
  • Adenocarcinoma, Clear Cell / genetics
  • Adenocarcinoma, Clear Cell / pathology*
  • Adult
  • Calmodulin-Binding Proteins / chemistry
  • Calmodulin-Binding Proteins / genetics
  • Carcinoma, Bronchogenic / chemistry
  • Carcinoma, Bronchogenic / genetics
  • Carcinoma, Bronchogenic / pathology*
  • Gene Rearrangement
  • Humans
  • Immunodominant Epitopes / analysis
  • Immunohistochemistry
  • Keratin-7 / analysis
  • Keratins, Hair-Specific / analysis
  • Lung Neoplasms / chemistry
  • Lung Neoplasms / genetics
  • Lung Neoplasms / pathology*
  • Male
  • Membrane Proteins / analysis
  • Peptide Fragments / analysis
  • RNA-Binding Protein EWS
  • RNA-Binding Proteins / chemistry
  • RNA-Binding Proteins / genetics

Substances

  • CKAP4 protein, human
  • Calmodulin-Binding Proteins
  • EWSR1 protein, human
  • Immunodominant Epitopes
  • KRTAP1-3 protein, human
  • Keratin-7
  • Keratins, Hair-Specific
  • Membrane Proteins
  • P40, iodinated C-terminal peptide, human
  • Peptide Fragments
  • RNA-Binding Protein EWS
  • RNA-Binding Proteins