Intraosseous benign leiomyoma is a rare manifestation of disseminated leiomyomatosis. In a 54 year old housewife presenting with a painful left hip due to a cystic lesion of the femoral neck, histological assessment following resection of the cyst showed a benign intraosseous leiomyoma. Years before a diagnosis of disseminated peritoneal leiomyomatosis had been made.