Skene's duct cysts are rare. A review of the medical literature revealed Skene's duct cysts in 2 newborns and 1 adult in whom the cyst caused superficial external dyspareunia. A case of Skene's duct cyst is reported, which was associated with spraying of the urinary stream during voiding. Differential diagnosis includes urethral diverticulum, ectopic ureterocele, cystocele and Gartner's duct cyst.