Copy number variation analysis of twin pairs discordant for cleft lip with or without cleft palate

Int J Immunopathol Pharmacol. 2019 Jan-Dec:33:2058738419855873. doi: 10.1177/2058738419855873.

Abstract

Non-syndromic cleft lip with or without cleft palate (nsCL/P) is a frequent orofacial malformation. The comparison of concordance rate observed in monozygotic and dizygotic twins supports high level of heritability and a strong genetic component. However, phenotype concordance for orofacial cleft in monozygotic twins is about 50%. The aim of the present investigation was to detect postzygotic events that may account for discordance in monozygotic twins. High-density SNP microarrays hybridization was used to genotype two pairs of monozygotic twins discordant for nsCL/P. Discordant SNP genotypes and copy number variants were analyzed to identify genetic differences responsible of phenotype discrepancy. A number of differences were observed, none involving known nsCL/P candidate genes or genomic regions. Considering the limitation of the study, related to the small sample size and to the large-scale investigation method, the results suggest that the detection of discordant events in other monozygotic twin pairs would be remarkable and warrant further investigations.

Keywords: cleft lip; cleft palate; monozygotic twins.

MeSH terms

  • Cleft Lip / genetics*
  • Cleft Palate / genetics*
  • DNA Copy Number Variations / genetics*
  • Genotype
  • Humans
  • Phenotype
  • Polymorphism, Single Nucleotide / genetics
  • Twins, Dizygotic / genetics*
  • Twins, Monozygotic / genetics*