MALDI imaging in Fabry nephropathy: a multicenter study

J Nephrol. 2020 Apr;33(2):299-306. doi: 10.1007/s40620-019-00627-w. Epub 2019 Jul 10.

Abstract

Background: The current study evaluates the application of histology and in situ proteomics (MALDI-MSI) in Fabry nephropathy (FN), showing investigative and classification role for this coupled approach.

Methods: A retrospective series of 14 formalin fixed paraffin embedded (FFPE) renal biopsies with diagnosis of FN and 1 biopsy from a patient bearing a galactosidase-α (GLA) genetic variant of unknown significance (GVUS, c.376A>G) have been classified for clinical characteristics. Groups were compared for histological differences (following the ISGFN scoring system). Moreover, renal biopsies from these cases have been analyzed with MALDI-MSI as previously described to find proteomic signatures among different mutations and phenotypes.

Results: Comparison of clinical features revealed lower mean 24 h proteinuria in females (225 mg/24 h) than in males (1477.5 mg/24 h, p = 0.006). As for clinical characteristics, females significantly differed from males only for lower arterial sclerosis, with a mean value of 0.82 vs. 1.05 (p = 0.001). Proteomic analysis demonstrated specific signatures in different subgroups of FN patients. Moreover, MALDI correctly classified cases with undetermined mutation or GVUS.

Conclusions: The present study demonstrated the feasible application of MALDI-MSI in the analysis of FN FFPE renal biopsies, allowing the detection of putative signatures for phenotypic distinction and demonstrating genetic classification capabilities.

Keywords: Fabry nephropathy; MALDI imaging; Proteomics; Renal biopsy.

Publication types

  • Multicenter Study

MeSH terms

  • Adult
  • Aged
  • Fabry Disease / diagnostic imaging*
  • Fabry Disease / genetics
  • Fabry Disease / pathology*
  • Female
  • Humans
  • Kidney Diseases / diagnostic imaging*
  • Kidney Diseases / genetics
  • Kidney Diseases / pathology*
  • Male
  • Middle Aged
  • Mutation
  • Proteomics
  • Retrospective Studies
  • Sex Factors
  • Spectrometry, Mass, Matrix-Assisted Laser Desorption-Ionization*
  • Young Adult