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    MFN2 mitofusin 2 [ Homo sapiens (human) ]

    Gene ID: 9927, updated on 22-May-2013
    Official Symbol
    MFN2provided by HGNC
    Official Full Name
    mitofusin 2provided by HGNC
    Primary source
    HGNC:16877
    Locus tag
    RP5-1077B9.3
    See related
    Ensembl:ENSG00000116688; HPRD:08495; MIM:608507; Vega:OTTHUMG00000002392
    Gene type
    protein coding
    RefSeq status
    REVIEWED
    Organism
    Homo sapiens
    Lineage
    Eukaryota; Metazoa; Chordata; Craniata; Vertebrata; Euteleostomi; Mammalia; Eutheria; Euarchontoglires; Primates; Haplorrhini; Catarrhini; Hominidae; Homo
    Also known as
    HSG; MARF; CMT2A; CPRP1; CMT2A2
    Summary
    This gene encodes a mitochondrial membrane protein that participates in mitochondrial fusion and contributes to the maintenance and operation of the mitochondrial network. This protein is involved in the regulation of vascular smooth muscle cell proliferation, and it may play a role in the pathophysiology of obesity. Mutations in this gene cause Charcot-Marie-Tooth disease type 2A2, and hereditary motor and sensory neuropathy VI, which are both disorders of the peripheral nervous system. Defects in this gene have also been associated with early-onset stroke. Two transcript variants encoding the same protein have been identified. [provided by RefSeq, Jul 2008]
    Location :
    1p36.22
    Sequence :
    Chromosome: 1; NC_000001.10 (12040238..12073572)
    See MFN2 in Epigenomics, MapViewer

    Chromosome 1 - NC_000001.10Genomic Context describing neighboring genes Neighboring gene KIAA2013 Neighboring gene procollagen-lysine, 2-oxoglutarate 5-dioxygenase 1 Neighboring gene migration and invasion inhibitory protein Neighboring gene tumor necrosis factor receptor superfamily, member 8

    GeneRIFs: Gene References Into Functions What's a GeneRIF?

    Charcot-Marie-Tooth disease, type 2A2

    Summary from GeneReviews: Charcot-Marie-Tooth Neuropathy Type 2 Go to GeneReviews

    Disease Characteristics
    Charcot-Marie-Tooth hereditary neuropathy type 2 (CMT2) is an axonal (non-demyelinating) peripheral neuropathy characterized by distal muscle weakness and atrophy, mild sensory loss, and normal or near-normal nerve conduction velocities. CMT2 is clinically similar to CMT1, although typically less severe. Peripheral nerves are not enlarged or hypertrophic. The subtypes of CMT2 are similar clinically and distinguished only by molecular genetic findings.
    Diagnosis Testing
    The diagnosis is based on clinical findings and EMG/NCV characteristics. The 15 genes in which mutations are known to cause CMT2 subtypes are KIF1B (CMT2A1), MFN2 (CMT2A2), RAB7A (formerly RAB7) (CMT2B), LMNA (CMT2B1), MED25 (CMT2B2), TRPV4 (CMTC), GARS (CMT2D), NEFL (CMT2E/1F), HSPB1 (CMT2F), MPZ (CMT2I/J), GDAP1 (CMT2H/K), HSPB8 (CMT2L), AARS (CMT2N), DYNC1H1 (CMT2O), and LRSAM1 (CMT2P). Molecular genetic testing is clinically available for CMT subtypes 2A1, 2A2, 2B, 2B1, 2B2, 2C, 2D, 2E, 2F, 2I, 2J, 2H/K, 2L, 2N, 2O, and 2P.
    Genetic Counseling
    CMT2B1, CMT2B2, and CMT2H/K are inherited in an autosomal recessive manner; all other subtypes of CMT2 are inherited in an autosomal dominant manner. Most probands with autosomal dominant subtypes of CMT2 have inherited the disease-causing mutation from an affected parent. The offspring of an affected individual with autosomal dominant CMT2 are at a 50% risk of inheriting the altered gene. Availability of prenatal diagnosis varies by subtype.
    References

    Summary from GeneReviews: Charcot-Marie-Tooth Neuropathy Type 2A Go to GeneReviews

    Disease Characteristics
    Charcot-Marie-Tooth hereditary neuropathy type 2A (CMT2A) is a classic axonal peripheral sensorimotor neuropathy characterized by earlier and more severe involvement of the lower extremities than the upper extremities, distal upper-extremity involvement as the neuropathy progresses, more prominent motor deficits than sensory deficits, and normal (>42 m/s) or only slightly decreased nerve conduction velocities (NCVs). Postural tremor is common. Most affected individuals develop symptoms in the first orf second decade. Although some individuals become dependent on crutches or a wheelchair, most do not.
    Diagnosis Testing
    The diagnosis is established by clinical and molecular genetic findings. MFN2, associated with the subtype CMT2A2, is the major gene known to be associated with CMT2A. KIF1B is associated with the subtype CMT2A1. Molecular genetic testing of both genes is available on a clinical basis.
    Genetic Counseling
    CMT2A is inherited in an autosomal dominant manner. Most individuals diagnosed with CMT2A have an affected parent. The proportion of cases caused by de novo mutations is unknown. Each child of an individual with CMT2A has a 50% chance of inheriting the mutation. Prenatal diagnosis for pregnancies at increased risk for CMT2A caused by MFN2 mutations is possible if the disease-causing mutation has been identified in an affected family member; prenatal diagnosis for pregnancies at risk for CMT2A caused by KIF1B mutations may be available through laboratories offering custom prenatal testing if the disease-causing mutation has been identified in an affected family member.
    References
    Protein Gene Interaction Pubs
    Vpr, p15 vpr HIV-1 Vpr significantly downregulates expression level of MFN2 in the mitochondria via VprBP-DDB1-CUL4A ubiquitin ligase in a proteasome-dependent manner PubMed

    Go to the HIV-1, Human Protein Interaction Database

    Products Interactant Other Gene Complex Source Pubs Description
    O95140 Q9NX47 MARCH5    HPRD  PubMed  
    BioGRID:115255 BioGRID:115385 HUWE1    BioGRID  PubMed Affinity Capture-Western 
    BioGRID:115255 BioGRID:111587 MAPK9    BioGRID  PubMed Affinity Capture-Western 
    BioGRID:115255 BioGRID:111105 PARK2    BioGRID  PubMed Affinity Capture-MS; Affinity Capture-Western 
    BioGRID:115255 BioGRID:131065 RGAG4    BioGRID  PubMed Affinity Capture-Western 
    BioGRID:115255 BioGRID:113164 UBC    BioGRID  PubMed Affinity Capture-MS; Affinity Capture-Western 
    BioGRID:115255 BioGRID:1205540 vpr    BioGRID  PubMed Affinity Capture-Western 
    • Factors involved in megakaryocyte development and platelet production, organism-specific biosystem (from REACTOME)
      Factors involved in megakaryocyte development and platelet production, organism-specific biosystemMegakaryocytes (MKs) give rise to circulating platelets (thrombocytes) through terminal differentiation of MKs which release cytoplasmic fragments as circulating platelets. As MKs mature they underg...
    • Hemostasis, organism-specific biosystem (from REACTOME)
      Hemostasis, organism-specific biosystemHemostasis is a physiological response that culminates in the arrest of bleeding from an injured vessel. Under normal conditions the vascular endothelium supports vasodilation, inhibits platelet adhe...

    Markers

    Homology

    Clone Names

    • KIAA0214

    Gene Ontology Provided by GOA

    Function Evidence Code Pubs
    GTP binding IEA
    Inferred from Electronic Annotation
    more info
     
    GTPase activity IEA
    Inferred from Electronic Annotation
    more info
     
    protein binding IPI
    Inferred from Physical Interaction
    more info
    PubMed 
    ubiquitin protein ligase binding IPI
    Inferred from Physical Interaction
    more info
    PubMed 
    Process Evidence Code Pubs
    blastocyst formation IEA
    Inferred from Electronic Annotation
    more info
     
    blood coagulation TAS
    Traceable Author Statement
    more info
     
    camera-type eye morphogenesis IEA
    Inferred from Electronic Annotation
    more info
     
    NOT cell cycle arrest ISS
    Inferred from Sequence or Structural Similarity
    more info
     
    mitochondrial fusion NAS
    Non-traceable Author Statement
    more info
    PubMed 
    mitochondrial membrane organization IDA
    Inferred from Direct Assay
    more info
    PubMed 
    mitochondrion localization IDA
    Inferred from Direct Assay
    more info
    PubMed 
    negative regulation of Ras protein signal transduction IDA
    Inferred from Direct Assay
    more info
    PubMed 
    negative regulation of smooth muscle cell proliferation ISS
    Inferred from Sequence or Structural Similarity
    more info
     
    protein targeting to mitochondrion IDA
    Inferred from Direct Assay
    more info
    PubMed 
    Component Evidence Code Pubs
    cytosol ISS
    Inferred from Sequence or Structural Similarity
    more info
     
    integral to membrane IEA
    Inferred from Electronic Annotation
    more info
     
    intrinsic to mitochondrial outer membrane ISS
    Inferred from Sequence or Structural Similarity
    more info
     
    microtubule cytoskeleton IEA
    Inferred from Electronic Annotation
    more info
     
    mitochondrial outer membrane TAS
    Traceable Author Statement
    more info
     
    mitochondrion IDA
    Inferred from Direct Assay
    more info
    PubMed 
    Preferred Names
    mitofusin-2
    Names
    mitofusin-2
    hyperplasia suppressor
    transmembrane GTPase MFN2
    mitochondrial assembly regulatory factor

    RefSeqs maintained independently of Annotated Genomes

    These reference sequences exist independently of genome builds. Explain

    These reference sequences are curated independently of the genome annotation cycle, so their versions may not match the RefSeq versions in the current genome build. Identify version mismatches by comparing the version of the RefSeq in this section to the one reported in Genomic regions, transcripts, and products above.

    Genomic

    1. NG_007945.1 RefSeqGene

      Range
      5001..38335
      Download
      GenBank, FASTA, Sequence Viewer (Graphics), LRG_255

    mRNA and Protein(s)

    1. NM_001127660.1NP_001121132.1  mitofusin-2

      Status: REVIEWED

      Description
      Transcript Variant: This variant (2) differs in the 5' UTR compared to variant 1. Both variants 1 and 2 encode the same protein.
      Source sequence(s)
      AI857365, AK289828, AL137666, DC401346
      Consensus CDS
      CCDS30587.1
      UniProtKB/Swiss-Prot
      O95140
      Related
      ENSP00000416338, ENST00000444836
      Conserved Domains (3) summary
      pfam04799
      Location:586756
      Blast Score: 707
      Fzo_mitofusin; fzo-like conserved region
      pfam00350
      Location:99258
      Blast Score: 265
      Dynamin_N; Dynamin family
      cd09912
      Location:97325
      Blast Score: 401
      DLP_2; Dynamin-like protein including dynamins, mitofusins, and guanylate-binding proteins
    2. NM_014874.3NP_055689.1  mitofusin-2

      Status: REVIEWED

      Description
      Transcript Variant: This variant (1) represents the longer transcript. Both variants 1 and 2 encode the same protein.
      Source sequence(s)
      AI857365, AL137666, BC017061, DC401346
      Consensus CDS
      CCDS30587.1
      UniProtKB/Swiss-Prot
      O95140
      Related
      ENSP00000235329, OTTHUMP00000002509, ENST00000235329, OTTHUMT00000006859
      Conserved Domains (3) summary
      pfam04799
      Location:586756
      Blast Score: 707
      Fzo_mitofusin; fzo-like conserved region
      pfam00350
      Location:99258
      Blast Score: 265
      Dynamin_N; Dynamin family
      cd09912
      Location:97325
      Blast Score: 401
      DLP_2; Dynamin-like protein including dynamins, mitofusins, and guanylate-binding proteins

    RefSeqs of Annotated Genomes: Homo sapiens Annotation Release 104

    The following sections contain reference sequences that belong to a specific genome build. Explain

    Reference GRCh37.p10 Primary Assembly

    Genomic

    1. NC_000001.10 Reference GRCh37.p10 Primary Assembly

      Range
      12040238..12073572
      Download
      GenBank, FASTA, Sequence Viewer (Graphics)

    Alternate HuRef

    Genomic

    1. AC_000133.1 Alternate HuRef

      Range
      11195001..11228266
      Download
      GenBank, FASTA, Sequence Viewer (Graphics)

    Alternate CHM1_1.0

    Genomic

    1. NC_018912.1 Alternate CHM1_1.0

      Range
      12058511..12091887
      Download
      GenBank, FASTA, Sequence Viewer (Graphics)

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