Display Settings:

Format

Send to:

Choose Destination
We are sorry, but NCBI web applications do not support your browser and may not function properly. More information

    GALT galactose-1-phosphate uridylyltransferase [ Homo sapiens (human) ]

    Gene ID: 2592, updated on 22-May-2013
    Official Symbol
    GALTprovided by HGNC
    Official Full Name
    galactose-1-phosphate uridylyltransferaseprovided by HGNC
    Primary source
    HGNC:4135
    Locus tag
    hCG_2040046
    See related
    Ensembl:ENSG00000213930; HPRD:06106; MIM:606999
    Gene type
    protein coding
    RefSeq status
    REVIEWED
    Organism
    Homo sapiens
    Lineage
    Eukaryota; Metazoa; Chordata; Craniata; Vertebrata; Euteleostomi; Mammalia; Eutheria; Euarchontoglires; Primates; Haplorrhini; Catarrhini; Hominidae; Homo
    Summary
    Galactose-1-phosphate uridyl transferase (GALT) catalyzes the second step of the Leloir pathway of galactose metabolism, namely the conversion of UDP-glucose + galactose-1-phosphate to glucose-1-phosphate + UDP-galactose. The absence of this enzyme results in classic galactosemia in humans and can be fatal in the newborn period if lactose is not removed from the diet. The pathophysiology of galactosemia has not been clearly defined. Two transcript variants encoding different isoforms have been found for this gene. [provided by RefSeq, Apr 2012]
    Location :
    9p13
    Sequence :
    Chromosome: 9; NC_000009.11 (34646586..34650595)
    See GALT in Epigenomics, MapViewer

    Chromosome 9 - NC_000009.11Genomic Context describing neighboring genes Neighboring gene AT rich interactive domain 3C (BRIGHT-like) Neighboring gene sigma non-opioid intracellular receptor 1 Neighboring gene interleukin 11 receptor, alpha Neighboring gene uncharacterized LOC730098 Neighboring gene chemokine (C-C motif) ligand 27

    GeneRIFs: Gene References Into Functions What's a GeneRIF?

    Deficiency of UDPglucose-hexose-1-phosphate uridylyltransferase

    Summary from GeneReviews: Galactosemia Go to GeneReviews

    Disease Characteristics
    Galactosemia is a disorder of galactose metabolism that can result in life-threatening complications including feeding problems, failure to thrive, hepatocellular damage, bleeding, and sepsis in untreated infants. If a lactose/galactose-restricted diet is provided during the first ten days of life, the neonatal symptoms quickly resolve and the complications of liver failure, sepsis, neonatal death, and intellectual disability can be prevented. Despite adequate treatment from an early age, children with galactosemia remain at increased risk for developmental delays, speech problems (termed "verbal dyspraxia"), and abnormalities of motor function. A female with galactosemia is at increased risk for premature ovarian insufficiency.
    Diagnosis Testing
    The diagnosis of galactosemia is established by measurement of erythrocyte galactose-1-phosphate uridyltransferase (GALT) enzyme activity, erythrocyte galactose-1-phosphate (gal-1-P) concentration, and GALT molecular genetic testing. In classic (G/G) galactosemia, GALT enzyme activity is less than 5% of control values and erythrocyte gal-1-P is higher than 10 mg/dL; in Duarte variant (D/G) galactosemia, GALT enzyme activity is usually higher 5% and approximates 25% of control values. Molecular genetic testing of GALT, the gene encoding galactose-1-phosphate uridyltransferase, is clinically available. Virtually 100% of affected infants can be detected in states that include testing for galactosemia in their newborn screening programs.
    Genetic Counseling
    Galactosemia is inherited in an autosomal recessive manner. Couples who have had one affected child have a 25% chance of having an affected child in each subsequent pregnancy. Prenatal diagnosis is possible for pregnancies at 25% risk for classic galactosemia using molecular genetic testing if the disease-causing GALT mutations in the family are known. If the disease-causing GALT mutations in a family are not known, GALT enzyme activity may be assayed in cultured amniotic fluid cells.
    References
    Products Interactant Other Gene Complex Source Pubs Description
    P07902 Q15645 TRIP13    HPRD  PubMed  
    BioGRID:108864 BioGRID:120115 TMED9    BioGRID  PubMed Co-fractionation 
    BioGRID:108864 BioGRID:114730 TRIP13    BioGRID  PubMed Two-hybrid 
    BioGRID:108864 BioGRID:113164 UBC    BioGRID  PubMed Affinity Capture-MS 

    Markers

    Potential readthrough

    Included gene: IL11RA

    Homology

    Gene Ontology Provided by GOA

    Function Evidence Code Pubs
    UDP-glucose:hexose-1-phosphate uridylyltransferase activity IEA
    Inferred from Electronic Annotation
    more info
     
    zinc ion binding IEA
    Inferred from Electronic Annotation
    more info
     
    Process Evidence Code Pubs
    UDP-glucose catabolic process IEA
    Inferred from Electronic Annotation
    more info
     
    carbohydrate metabolic process TAS
    Traceable Author Statement
    more info
     
    galactose catabolic process TAS
    Traceable Author Statement
    more info
     
    galactose metabolic process TAS
    Traceable Author Statement
    more info
    PubMed 
    small molecule metabolic process TAS
    Traceable Author Statement
    more info
     
    Component Evidence Code Pubs
    Golgi apparatus IDA
    Inferred from Direct Assay
    more info
     
    cytosol TAS
    Traceable Author Statement
    more info
     
    Preferred Names
    galactose-1-phosphate uridylyltransferase
    Names
    galactose-1-phosphate uridylyltransferase
    gal-1-P uridylyltransferase
    galactose-1-phosphate uridyl transferase
    UDP-glucose--hexose-1-phosphate uridylyltransferase
    NP_000146.1
    NP_000146.2
    NP_001245261.1

    RefSeqs maintained independently of Annotated Genomes

    These reference sequences exist independently of genome builds. Explain

    These reference sequences are curated independently of the genome annotation cycle, so their versions may not match the RefSeq versions in the current genome build. Identify version mismatches by comparing the version of the RefSeq in this section to the one reported in Genomic regions, transcripts, and products above.

    Genomic

    1. NG_009029.1 RefSeqGene

      Range
      4952..8961
      Download
      GenBank, FASTA, Sequence Viewer (Graphics)

    mRNA and Protein(s)

    1. NM_000155.3NP_000146.2  galactose-1-phosphate uridylyltransferase isoform 1

      Status: REVIEWED

      Description
      Transcript Variant: This variant (1) represents the longer transcript and encodes the longer isoform (1).
      Source sequence(s)
      AI292159, AK314340, BC015045, DA011092
      Consensus CDS
      CCDS6565.1
      UniProtKB/TrEMBL
      B2RAT6
      UniProtKB/Swiss-Prot
      P07902
      Conserved Domains (2) summary
      cd00608
      Location:31361
      Blast Score: 1093
      GalT; Galactose-1-phosphate uridyl transferase (GalT): This enzyme plays a key role in galactose metabolism by catalysing the transfer of a uridine 5'-phosphoryl group from UDP-galactose 1-phosphate. The structure of E.coli GalT reveals that the enzyme ...
      PRK11720
      Location:23366
      Blast Score: 1488
      PRK11720; galactose-1-phosphate uridylyltransferase; Provisional
    2. NM_001258332.1NP_001245261.1  galactose-1-phosphate uridylyltransferase isoform 2

      Status: REVIEWED

      Description
      Transcript Variant: This variant (2) lacks two alternate coding exons compared to variant 1, that causes a frameshift. The resulting isoform (2) has a shorter and distinct N-terminus compared to isoform 1.
      Source sequence(s)
      AI292159, AK303279, AK314340, DA011092
      Consensus CDS
      CCDS59122.1
      UniProtKB/TrEMBL
      B2RAT6
      UniProtKB/Swiss-Prot
      P07902
      Related
      ENSP00000401956, ENST00000450095
      Conserved Domains (1) summary
      cd00608
      Location:17252
      Blast Score: 787
      GalT; Galactose-1-phosphate uridyl transferase (GalT): This enzyme plays a key role in galactose metabolism by catalysing the transfer of a uridine 5'-phosphoryl group from UDP-galactose 1-phosphate. The structure of E.coli GalT reveals that the enzyme ...

    RefSeqs of Annotated Genomes: Homo sapiens Annotation Release 104

    The following sections contain reference sequences that belong to a specific genome build. Explain

    Reference GRCh37.p10 Primary Assembly

    Genomic

    1. NC_000009.11 Reference GRCh37.p10 Primary Assembly

      Range
      34646586..34650595
      Download
      GenBank, FASTA, Sequence Viewer (Graphics)

    Alternate HuRef

    Genomic

    1. AC_000141.1 Alternate HuRef

      Range
      34600857..34604875
      Download
      GenBank, FASTA, Sequence Viewer (Graphics)

    Alternate CHM1_1.0

    Genomic

    1. NC_018920.1 Alternate CHM1_1.0

      Range
      34615072..34619081
      Download
      GenBank, FASTA, Sequence Viewer (Graphics)

      Supplemental Content

      Recent activity

      Your browsing activity is empty.

      Activity recording is turned off.

      Turn recording back on

      See more...